Tularemia is caused by a small, Gram-negative, pleomorphic coccobacillus, Francisella tularensis. Oculoglandular tularemia is a rare clinical form. There are few reports about oculoglandular tularemia, and less than 20 cases with oculoglandular tularemia have been reported in PubMed up to date We reviewed the literature about oculoglandular tularemia, and reported a 31-year-old woman with oculoglandular and oropharyngeal tularemia She admitted to our hospital with a three-week history of sudden onset of fever, fatigue, headache, sore throat, swollen left upper lid, injected and erythematous left eye, epiphora, preauricular nontender lump on the left and generalized aches, but there was no history of eye injury She was living in a village where tularemia is endemic, but no history of encountering with an animal The clinical diagnosis of oculoglandular and orophayngeal tularemia was confirmed by microagglutination test and PCR She was fully improved on the eighth day of the ciprofloxacine treatment Tularemia should come to mind in patients with fever, severe throat, conjunctivitis and cervical masses especially unresponsive to penicillin or cephalosporine therapy, coming from a tularemia endemic area